Osteochondroma of the sigmoide notch: a case report of an unusual location

  • Ana Reis Durão Universidade do Porto
  • Israel Chilvarquer Universidade de São Paulo
  • Márcia Provenzano Universidade de São Paulo
  • José T Koch Universidade do Porto
  • Marcelo Miranda Universidade do Porto
  • Aline Cantarelli Morosolli Pontifícia Universidade Católica do Rio Grande do Sul
Keywords: Osteochondroma, Sigmoid notch, Facial asymmetry, Restricted mouth opening


Objective: This article presents an interesting case of osteochondroma of the the sigmoid notch.
Case Report: A 15-year-old female with severe facial asymmetry, malocclusion, open bite and extreme limitation of mouth opening. Panoramic radiography showed an exophytic radiopaque mass arising from the sigmoid notch on the right side. CT images revealed bony proliferation with benign signs causing damage to the articular eminence, condilar morphology and periarticular soft tissue calcifications. Magnetic Resonance confirmed the findings of the CT and revealed modifications on disc morphology. A surgical resection was performed.
Conclusion: The OC located at the sigmoid notch presented is probably the rarest site seen in the existing literature.


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Case Report